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Table 1 Summary of all the selected studies

From: The male-to-female ratio in late-onset multiple acyl-CoA dehydrogenase deficiency: a systematic review and meta-analysis

First author

Publication year

Study period

Country

Sample size

HDI

MFR of general population

Shimizu [e47]

1991

NR

Japan

5

Very high

0.95:1

Russell [e48]

2003

NR

Italy

7

Very high

0.95:1

Yang [e49]

2004

2000–2003

China

7

High

1.06:1

Olsen [19]

2007

1998–2006

Denmark

15

Very high

0.99:1

Er [e50]

2010

NR

China

9

High

1.06:1

Lan [e51]

2010

2001–2008

China

9

High

1.06:1

Wang [8]

2011

NR

China

56

High

1.06:1

Wang [e52]

2011

2003–2010

China

24

High

1.06:1

Xi [e53]

2011

2005–2010

China

31

High

1.06:1

Liu [e54]

2012

NR

China

8

High

1.06:1

Fang [e55]

2014

2008–2013

China

5

High

1.06:1

Zhu [9]

2014

2011–2013

China

13

High

1.06:1

Béhin [20]

2016

NR

France

13

Very high

0.93:1

Liu [e56]

2016

2012–2015

China

28

High

1.06:1

Olsen [e57]

2016

NR

Denmark

7

Very high

0.99:1

Angelini [e58]

2018

NR

Italy

6

Very high

0.95:1

Zhao [15]

2018

2013–2016

China

25

High

1.06:1

Henriques [e59]

2019

NR

Portugal

5

Very high

0.95:1

Hong [17]

2019

2014–2018

China

25

High

1.06:1

Nilipour [18]

2020

2011–2016

Iran

19

High

0.99:1

Sun [e60]

2020

2012–2017

China

5

High

1.06:1

Yildiz [e61]

2020

NR

Turkey

20

Very high

1:1

Yuan [e62]

2020

2009–2019

China

15

High

1.06:1

Ali [e63]

2021

2009–2020

United Arab Emirates

11

Very high

2.26:1

Kuo [e64]

2021

1998–2018

China

6

High

1.06:1

Staretz-Chacham [e65]

2021

NR

Israel

5

Very high

1:1

Tang [e66]

2021

2018–2021

China

5

High

1.06:1

Liu [e67]

2022

2009–2021

China

26

High

1.06:1

Lupica [e68]

2022

2001–2021

Italy

10

Very high

0.95:1

Wen [5]

2022

1995–2019

China

110

High

1.06:1

Yamada [e69]

2022

1997–2020

Japan

22

Very high

0.95:1

Zhang [e70]

2022

2005–2020

China

31

High

1.06:1

Zheng [16]

2022

2019–2021

China

13

High

1.06:1

Zhang [6]

2023

2016–2022

China

13

High

1.06:1

  1. Legend: HDI, Human Development Index; MFR, male to female ratio; NR, not reported