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Table 3 Test–retest reliability (kappa coefficient) for main analysis

From: Development and evaluation of a patient-reported outcome measure specific for Gaucher disease with or without neurological symptoms in Japan

Item

Overall

GD1

GD2

GD3

n

Estimate (95% CI)

n

Estimate (95% CI)

n

Estimate (95% CI)

n

Estimate (95% CI)

Part 1

P1-1

22

0.446 (−0.112, 1)

7

0.774 (0.774, 0.774)

9

−0.438 (−1, 1)

6

0.889 (0.714, 1)

P1-2

26

0.349 (−1, 1)

8

NA

10

−0.067 (−1, 1)

8

0.842 (0.842, 0.842)

P1-3

10

0.828 (0.828, 0.828)

4

NA

2

NA

4

0.750 (0.577, 0.923)

P1-4

27

0.468 (−0.158, 1)

8

NA

10

−0.067 (−1, 1)

9

0.787 (0.561, 1)

P1-5

25

0.556 (0.269, 0.844)

8

− 0.111 (−1, 1)

8

0.481 (−0.355, 1)

9

0.471 (−0.199, 1)

P1-6

28

0.612 (0.486, 0.738)

8

0.800 (0.800, 0.800)

11

0.193 (−0.775, 1)

9

0.769 (0.769, 0.769)

P1-7

24

0.286 (−1, 1)

8

0.778 (0.778, 0.778)

7

−0.235 (−1, 1)

9

0.542 (0.233, 0.852)

P1-8

26

0.438 (−0.788, 1)

8

0.373 (−1, 1)

9

0.091 (−0.847, 1)

9

0.890 (0.890, 0.890)

P1-9

23

0.390 (− 0.931, 1)

8

0.833 (0.833, 0.833)

7

0.222 (−1, 1)

8

0.517 (−0.179, 1)

P1-10

26

0.097 (−1, 1)

8

0.625 (0.625, 0.625)

10

−0.231 (−1, 1)

8

0.333 (−0.848, 1)

P1-11

28

0.487 (−1, 1)

8

0.867 (0.867, 0.867)

11

−0.039 (−1, 1)

9

0.679 (0.679, 0.679)

P1-12

24

0.538 (0.155, 0.922)

7

0.887 (0.705, 1)

8

0.132 (−1, 1)

9

0.518 (−0.365, 1)

P1-13

30

0.444 (−0.388, 1)

8

0.094 (−0.941, 1)

13

0.221 (−0.656, 1)

9

0.780 (0.780, 0.780)

P1-14

30

0.496 (−0.605, 1)

8

0.576 (−1, 1)

13

0.300 (−0.565, 1)

9

0.046 (−1, 1)

P1-15

30

0.608 (0.331, 0.884)

8

0.467 (−0.166, 1)

13

0.273 (−1, 1)

9

0.798 (0.798, 0.798)

Part 2

P2-1

29

0.971 (0.971, 0.971)

8

0.857 (0.857, 0.857)

12

0.175 (−1, 1)

9

0.976 (0.976, 0.976)

P2-2

29

0.562 (−1, 1)

7

0 (0, 0)

13

0.649 (0.649, 0.649)

9

0.434 (−1, 1)

P2-3

30

0.781 (0.781, 0.781)

8

0.364 (−0.215, 0.943)

13

0.787 (0.787, 0.787)

9

0.799 (0.799, 0.799)

P2-4

30

0.612 (0.612, 0.612)

8

0.298 (−0.500, 1)

13

0.363 (−0.397, 1)

9

0.917 (0.917, 0.917)

P2-5

30

0.746 (0.746, 0.746)

8

0.926 (0.926, 0.926)

13

0.483 (−1, 1)

9

0.900 (0.900, 0.900)

P2-6

30

0.630 (0.630, 0.630)

8

0.737 (0.737, 0.737)

13

0.458 (−0.287, 1)

9

0.739 (0.204, 1)

P2-7

30

0.658 (0.174, 1)

8

0.846 (0.846, 0.846)

13

0.703 (0.703, 0.703)

9

0.361 (−1, 1)

P2-8

30

0.582 (−0.003, 1)

8

0.793 (0.793, 0.793)

13

0.680 (0.172, 1)

9

0.247 (−1, 1)

P2-9

30

0.462 (−1, 1)

8

0.154 (−1, 1)

13

0.259 (−1, 1)

9

0.428 (−1, 1)

Part 3

P3-1

30

0.842 (0.842, 0.842)

8

0.769 (0.769, 0.769)

13

0.768 (0.768, 0.768)

9

0.967 (0.967, 0.967)

P3-2

30

0.683 (0.683, 0.683)

8

0.580 (−0.107, 1)

13

0.731 (0.731, 0.731)

9

0.749 (0.749, 0.749)

P3-3

30

0.868 (0.868, 0.868)

8

NA

13

0.786 (0.786, 0.786)

9

0.856 (0.856, 0.856)

P3-4

30

0.988 (0.988, 0.988)

8

0 (−1, 1)

13

0.988 (0.988, 0.988)

9

0.957 (0.957, 0.957)

P3-5

30

0.961 (0.961, 0.961)

8

0.760 (0.760, 0.760)

13

0.937 (0.937, 0.937)

9

0.942 (0.942, 0.942)

P3-6

29

0.855 (0.855, 0.855)

7

NA

13

0.869 (0.869, 0.869)

9

0.518 (−1, 1)

P3-7

30

0.803 (0.803, 0.803)

8

0.917 (0.917, 0.917)

13

0.692 (0.058, 1)

9

0.862 (0.862, 0.862)

P3-8

30

0.811 (0.811, 0.811)

8

0.609 (0.609, 0.609)

13

0.731 (0.731, 0.731)

9

0.947 (0.800, 1)

P3-9

30

0.266 (−1, 1)

8

0.191 (−0.206, 0.589)

13

0.248 (−0.665, 1)

9

0.286 (−0.0775, 1)

P3-10

30

0.659 (0.482, 0.835)

8

0.841 (0.600, 1)

13

0.511 (−0.486, 1)

9

0.654 (0.160, 1)

P3-11

30

0.536 (−1, 1)

8

0.167 (−1, 1)

13

0.277 (−1, 1)

9

0.930 (0.930, 0.930)

P3-12

29

0.608 (−0.024, 1)

8

0 (0, 0)

12

0.361 (−0.553, 1)

9

0.696 (0.048, 1)

P3-13

30

0.776 (0.776, 0.776)

8

0.632 (− 0.154, 1)

13

0.736 (0.359, 1)

9

0.860 (0.860, 0.860)

P3-14

30

0.782 (0.782, 0.782)

8

−0.070 (−1, 0.869)

13

0.759 (0.286, 1)

9

0.658 (0.658, 0.658)

P3-15

30

0.753 (0.753, 0.753)

8

−0.172 (−1, 1)

13

0.845 (0.845, 0.845)

9

0.657 (0.012, 1)

P3-16

27

0.514 (−0.255, 1)

6

0.848 (0.848, 0.848)

12

0.470 (−0.605, 1)

9

0.112 (−1, 1)

  1. Kappa coefficients > 0.6 are in bold; coefficients < 0.2 are in italics. In general, a kappa coefficient < 0.2 indicates no agreement, 0.2–0.4 indicates minimal agreement, 0.4–0.6 indicates weak agreement, 0.6–0.8 indicates moderate agreement, 0.8–0.9 indicates strong agreement, and > 0.9 indicates almost perfect agreement [29]
  2. CI: confidence interval; GD1/2/3: type 1/2/3 Gaucher disease; NA: not applicable; P: Part